Reference SummaryBardeesy N, Mol Cell Biol 2002 Jan;22(2):635-43

Title

Obligate roles for p16(Ink4a) and p19(Arf)-p53 in the suppression of murine pancreatic neoplasia.

Authors

Bardeesy N; Morgan J; Sinha M; Signoretti S; Srivastava S; Loda M; Merlino G; DePinho RA

Journal

Mol Cell Biol

Volume

22

Issue

2

Year

2002

Pages

635-43

Abstract

Epithelial tumors of the pancreas exhibit a wide spectrum of histologies with varying propensities for metastasis and tissue invasion. The histogenic relationship among these tumor types is not well established; moreover, the specific role of genetic lesions in the progression of these malignancies is largely undefined. Transgenic mice with ectopic expression of transforming growth factor alpha (TGF-alpha) in the pancreatic acinar cells develop tubular metaplasia, a potential premalignant lesion of the pancreatic ductal epithelium. To evaluate the cooperative interactions between TGF-alpha and signature mutations in pancreatic tumor genesis and progression, TGFalpha transgenic mice were crossed onto Ink4a/Arf and/or p53 mutant backgrounds. These compound mutant mice developed a novel pancreatic neoplasm, serous cystadenoma (SCA), presenting as large epithelial tumors bearing conspicuous gross and histological resemblances to their human counterpart. TGFalpha animals heterozygous for both the Ink4a/Arf and the p53 mutation showed a dramatically increased incidence of SCA, indicating synergistic interaction of these alleles. Inactivation of p16(Ink4a) by loss of heterozygosity, intragenic mutation, or promoter hypermethylation was a common feature in these SCAs, and correspondingly, none of the tumors expressed wild-type p16(Ink4a). All tumors sustained loss of p53 or Arf, generally in a mutually exclusive fashion. The tumor incidence data and molecular profiles establish a pathogenic role for the dual inactivation of p16(Ink4a) and p19(Arf)-p53 in the development of SCA in mice, demonstrating that p16(Ink4a) is a murine tumor suppressor. This genetically defined model provides insights into the molecular pathogenesis of SCA and serves as a platform for dissection of cell-specific programs of epithelial tumor suppression.

Links

J:73973 – MGI References
11756558 – National Library of Medicine/PubMed

Strain Notes

Strain Note
B6;CD-1-Tg(MtTGFA)42Lmb The genetic background of these mice was a mixture of C57BL/6 and CD-1.

Models

Strain Model Name Treatment Agent(s) Organ Affected Frequency Model Details
STOCK Cdkn2atm1Rdp/+ Leukocyte lymphoma Leukocyte

observed

STOCK Cdkn2atm1Rdp Leukocyte lymphoma Leukocyte

observed

FVB/N-Tg(MtTGFA)100Lmb Liver - Bile duct hyperplasia Liver - Bile duct

observed

B6;CD-1-Tg(MtTGFA)42Lmb Liver hepatocellular carcinoma Liver

observed

STOCK Cdkn2atm1Rdp/+ Mesodermal cell/mesoblast sarcoma Mesodermal cell/mesoblast

observed

STOCK Cdkn2atm1Rdp Mesodermal cell/mesoblast sarcoma Mesodermal cell/mesoblast

observed

STOCK Cdkn2atm1Rdp Tg(MtTGFA)42Lmb Pancreas cystadenoma - serous Pancreas

12

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Pancreas cystadenoma - serous Pancreas

3.0

STOCK Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ Pancreas cystadenoma - serous Pancreas

2.4

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ Pancreas cystadenoma - serous Pancreas

35

STOCK Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas cystadenoma - serous Pancreas

27

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas cystadenoma - serous Pancreas

30

STOCK Cdkn2atm1Rdp Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas cystadenoma - serous Pancreas

25

FVB/N-Tg(MtTGFA)100Lmb Pancreas cystadenoma - serous Pancreas

0

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)100Lmb Pancreas cystadenoma - serous Pancreas

42

STOCK Tg(MtTGFA)100Lmb Trp53tm1Tyj/+ Pancreas cystadenoma - serous Pancreas

50

STOCK Trp53tm1Tyj Pancreas cystadenoma - serous Pancreas

0

STOCK Cdkn2atm1Rdp/+ Trp53tm1Tyj/+ Pancreas cystadenoma - serous Pancreas

0

B6;CD-1-Tg(MtTGFA)42Lmb Pancreas metaplasia - tubular Pancreas

100

STOCK Cdkn2atm1Rdp Tg(MtTGFA)42Lmb Pancreas metaplasia - tubular Pancreas

observed

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Pancreas metaplasia - tubular Pancreas

observed

STOCK Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ Pancreas metaplasia - tubular Pancreas

observed

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ Pancreas metaplasia - tubular Pancreas

observed

STOCK Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas metaplasia - tubular Pancreas

observed

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas metaplasia - tubular Pancreas

observed

STOCK Cdkn2atm1Rdp Tg(MtTGFA)42Lmb Trp53tm1Tyj Pancreas metaplasia - tubular Pancreas

observed

FVB/N-Tg(MtTGFA)100Lmb Pancreas metaplasia - tubular Pancreas

observed

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)100Lmb Pancreas metaplasia - tubular Pancreas

observed

STOCK Tg(MtTGFA)100Lmb Trp53tm1Tyj/+ Pancreas metaplasia - tubular Pancreas

observed

B6;CD-1-Tg(MtTGFA)42Lmb Pancreas tumor Pancreas

0

STOCK Cdkn2atm1Rdp/+ Pancreas tumor Pancreas

0

STOCK Cdkn2atm1Rdp Pancreas tumor Pancreas

0

FVB/N-Tg(MtTGFA)100Lmb Stomach hyperplasia Stomach

observed

B6;CD-1-Tg(MtTGFA)42Lmb (Unspecified organ) tumor (Unspecified organ)

0

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb (Unspecified organ) tumor (Unspecified organ)

100

STOCK Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ (Unspecified organ) tumor (Unspecified organ)

100

STOCK Cdkn2atm1Rdp/+ Tg(MtTGFA)42Lmb Trp53tm1Tyj/+ (Unspecified organ) tumor (Unspecified organ)

91

STOCK Cdkn2atm1Rdp/+ (Unspecified organ) tumor (Unspecified organ)

100

STOCK Cdkn2atm1Rdp/+ Trp53tm1Tyj/+ (Unspecified organ) tumor (Unspecified organ)

57